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oligomeganephronia

Monday 12 March 2007

Oligomeganephronia (OMN) is a rare congenital and usually sporadic anomaly. It is characterized by bilateral renal hypoplasia, with a reduced number of enlarged nephrons. The mechanisms involved in this deficient nephrogenesis are unknown.

Associations

 distal limb deficiencies with micrognathia (MIM.246560)

Etiology

 PAX2 germline mutations (11168927)

See also

 paired box transcription factors (PAXs)

  • PAX2

 renal development
 renal hypoplasia
 retinal defects
 renal-coloboma syndrome

References

 Salomon R, Tellier AL, Attie-Bitach T, Amiel J, Vekemans M, Lyonnet S, Dureau P, Niaudet P, Gubler MC, Broyer M. PAX2 mutations in oligomeganephronia. Kidney Int. 2001 Feb;59(2):457-62. PMID: 11168927